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The PTEN and INK4A/ARF tumor suppressors maintain myelolymphoid homeostasis and cooperate to constrain histiocytic sarcoma development in humans.

The PTEN and INK4A/ARF tumor suppressors maintain myelolymphoid homeostasis and cooperate to constrain histiocytic sarcoma development in humans.
The PTEN and INK4A/ARF tumor suppressors maintain myelolymphoid homeostasis and cooperate to constrain histiocytic sarcoma development in humans.
Histiocytic sarcoma (HS) is a rare malignant proliferation of histiocytes of uncertain molecular pathogenesis. Here, genetic analysis of coincident loss of Pten and Ink4a/Arf tumor suppressors in the mouse revealed a neoplastic phenotype dominated by a premalignant expansion of biphenotypic myelolymphoid cells followed by the development of HS. Pten protein loss occurred only in the histiocytic portion of tumors, suggesting a stepwise genetic inactivation in the generation of HS. Similarly, human HS showed genetic or epigenetic inactivation of PTEN, p16(INK4A), and p14(ARF), supporting the relevance of this genetically engineered mouse model of HS. These genetic and translational observations establish a cooperative role of Pten and Ink4a/Arf in the development of HS and provide mechanistic insights into the pathogenesis of human HS.
Animals, Cyclin-Dependent Kinase Inhibitor p16, Enzyme Activation, Extracellular Signal-Regulated MAP Kinases, Histiocytic Disorders, Malignant, Homeostasis, Humans, Immunophenotyping, Lymphocytes, Methylation, Mice, Mutation, Myeloid Cells, PTEN Phosphohydrolase, Proto-Oncogene Proteins c-akt, Sarcoma, Tumor Suppressor Protein p14ARF
1535-6108
379-390
Carrasco, DR
2ab4f0b5-7844-47bc-944e-1aa755cadb01
Fenton, TR
087260ba-f6a1-405a-85df-099d05810a84
Sukhdeo, K
82a51c98-8e7f-49ff-a4f4-5df388e05df1
Protopopova, M
68a7fcdb-ad88-4022-96ec-85b7bb31b0dc
Enos, M
808357af-504a-418b-a1b1-745c9177a1a2
You, MJ
bc224ede-d628-4db1-a5a7-fe5de765e089
Vizio, D Di
89b434b8-1198-4055-9960-df451721ed5c
Nogueira, C
96685195-bac1-4b97-b1a7-9cd9a0bd269d
Stommel, J
54dc05a9-8408-4624-a35a-26f6fbbbcdef
Pinkus, GS
6eea20e9-6411-4e0d-b056-54df2daa6482
Fletcher, C
9697fe1b-9519-4801-b9bb-2b55c615265c
Hornick, JL
b93d7012-8cc6-4835-9706-cc2f33b7200c
Cavenee, WK
e92aa948-8cc9-419f-a596-b36ed9ceeb09
Furnari, FB
eb84de55-9ec1-480b-8424-11703ab8db3d
Depinho, RA
f71939ec-be48-4c2a-a67b-6873f8fb9b5f
Carrasco, DR
2ab4f0b5-7844-47bc-944e-1aa755cadb01
Fenton, TR
087260ba-f6a1-405a-85df-099d05810a84
Sukhdeo, K
82a51c98-8e7f-49ff-a4f4-5df388e05df1
Protopopova, M
68a7fcdb-ad88-4022-96ec-85b7bb31b0dc
Enos, M
808357af-504a-418b-a1b1-745c9177a1a2
You, MJ
bc224ede-d628-4db1-a5a7-fe5de765e089
Vizio, D Di
89b434b8-1198-4055-9960-df451721ed5c
Nogueira, C
96685195-bac1-4b97-b1a7-9cd9a0bd269d
Stommel, J
54dc05a9-8408-4624-a35a-26f6fbbbcdef
Pinkus, GS
6eea20e9-6411-4e0d-b056-54df2daa6482
Fletcher, C
9697fe1b-9519-4801-b9bb-2b55c615265c
Hornick, JL
b93d7012-8cc6-4835-9706-cc2f33b7200c
Cavenee, WK
e92aa948-8cc9-419f-a596-b36ed9ceeb09
Furnari, FB
eb84de55-9ec1-480b-8424-11703ab8db3d
Depinho, RA
f71939ec-be48-4c2a-a67b-6873f8fb9b5f

Carrasco, DR, Fenton, TR, Sukhdeo, K, Protopopova, M, Enos, M, You, MJ, Vizio, D Di, Nogueira, C, Stommel, J, Pinkus, GS, Fletcher, C, Hornick, JL, Cavenee, WK, Furnari, FB and Depinho, RA (2006) The PTEN and INK4A/ARF tumor suppressors maintain myelolymphoid homeostasis and cooperate to constrain histiocytic sarcoma development in humans. Cancer Cell, 9 (5), 379-390. (doi:10.1016/j.ccr.2006.03.028).

Record type: Article

Abstract

Histiocytic sarcoma (HS) is a rare malignant proliferation of histiocytes of uncertain molecular pathogenesis. Here, genetic analysis of coincident loss of Pten and Ink4a/Arf tumor suppressors in the mouse revealed a neoplastic phenotype dominated by a premalignant expansion of biphenotypic myelolymphoid cells followed by the development of HS. Pten protein loss occurred only in the histiocytic portion of tumors, suggesting a stepwise genetic inactivation in the generation of HS. Similarly, human HS showed genetic or epigenetic inactivation of PTEN, p16(INK4A), and p14(ARF), supporting the relevance of this genetically engineered mouse model of HS. These genetic and translational observations establish a cooperative role of Pten and Ink4a/Arf in the development of HS and provide mechanistic insights into the pathogenesis of human HS.

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More information

Accepted/In Press date: 10 March 2006
e-pub ahead of print date: 15 May 2006
Keywords: Animals, Cyclin-Dependent Kinase Inhibitor p16, Enzyme Activation, Extracellular Signal-Regulated MAP Kinases, Histiocytic Disorders, Malignant, Homeostasis, Humans, Immunophenotyping, Lymphocytes, Methylation, Mice, Mutation, Myeloid Cells, PTEN Phosphohydrolase, Proto-Oncogene Proteins c-akt, Sarcoma, Tumor Suppressor Protein p14ARF

Identifiers

Local EPrints ID: 453964
URI: http://eprints.soton.ac.uk/id/eprint/453964
ISSN: 1535-6108
PURE UUID: cda9545d-c59c-490d-80f7-f19104de6d42
ORCID for TR Fenton: ORCID iD orcid.org/0000-0002-4737-8233

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Date deposited: 26 Jan 2022 17:51
Last modified: 25 Sep 2024 02:01

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Contributors

Author: DR Carrasco
Author: TR Fenton ORCID iD
Author: K Sukhdeo
Author: M Protopopova
Author: M Enos
Author: MJ You
Author: D Di Vizio
Author: C Nogueira
Author: J Stommel
Author: GS Pinkus
Author: C Fletcher
Author: JL Hornick
Author: WK Cavenee
Author: FB Furnari
Author: RA Depinho

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