The University of Southampton
University of Southampton Institutional Repository

Identification of Cystic Lesions by Secondary Screening of Familial Pancreatic Cancer (FPC) Kindreds Is Not Associated with the Stratified Risk of Cancer

Identification of Cystic Lesions by Secondary Screening of Familial Pancreatic Cancer (FPC) Kindreds Is Not Associated with the Stratified Risk of Cancer
Identification of Cystic Lesions by Secondary Screening of Familial Pancreatic Cancer (FPC) Kindreds Is Not Associated with the Stratified Risk of Cancer

OBJECTIVES: Intraductal papillary mucinous neoplasms (IPMNs) are associated with risk of pancreatic ductal adenocarcinoma (PDAC). It is unclear if an IPMN in individuals at high risk of PDAC should be considered as a positive screening result or as an incidental finding. Stratified familial pancreatic cancer (FPC) populations were used to determine if IPMN risk is linked to familial risk of PDAC.

METHODS: This is a cohort study of 321 individuals from 258 kindreds suspected of being FPC and undergoing secondary screening for PDAC through the European Registry of Hereditary Pancreatitis and Familial Pancreatic Cancer (EUROPAC). Computerised tomography, endoscopic ultrasound of the pancreas and magnetic resonance imaging were used. The risk of being a carrier of a dominant mutation predisposing to pancreatic cancer was stratified into three even categories (low, medium and high) based on: Mendelian probability, the number of PDAC cases and the number of people at risk in a kindred.

RESULTS: There was a median (interquartile range (IQR)) follow-up of 2 (0-5) years and a median (IQR) number of investigations per participant of 4 (2-6). One PDAC, two low-grade neuroendocrine tumours and 41 cystic lesions were identified, including 23 IPMN (22 branch-duct (BD)). The PDAC case occurred in the top 10% of risk, and the BD-IPMN cases were evenly distributed amongst risk categories: low (6/107), medium (10/107) and high (6/107) (P = 0.63).

CONCLUSIONS: The risk of finding BD-IPMN was independent of genetic predisposition and so they should be managed according to guidelines for incidental finding of IPMN.

Adult, Aged, Aged, 80 and over, Carcinoma/epidemiology, Cohort Studies, Early Detection of Cancer, Europe/epidemiology, Family, Female, Genetic Predisposition to Disease, Humans, Male, Middle Aged, Pancreatic Neoplasms/epidemiology, Pedigree, Registries, Risk Factors, Young Adult
0002-9270
155-164
Sheel, A R G
e8016252-2679-4f8a-b90c-f2095dc5bc1e
Harrison, S
af66a0d9-ce76-4914-a9d8-61f86a998085
Sarantitis, I
1c0c58a4-e71f-492d-a84c-b81356de2794
Nicholson, J A
9043a0a9-5007-4e7a-b8b8-26d6264209c7
Hanna, T
627d1d69-d84a-4f8c-b66e-facbb8a535e5
Grocock, C
de9a400c-08df-4b8b-8565-45a662ae072f
Raraty, M
f4139609-edcc-4e91-a45d-916fb4788e05
Ramesh, J
78330a65-e11d-4a75-96f4-6a36669823ab
Farooq, A
dff97dc3-934c-44e1-9abf-2a77fbda36af
Costello, E
3c0fed5e-fed6-4cfa-b0c1-971fa047d58f
Jackson, R
6287549a-58f1-4ca1-a860-82b757935617
Chapman, M
6b799270-9f6a-4c63-b007-36ecff1a00c1
Carter, R
37d2ed73-da11-47f3-aa1c-c566c1e0814f
Mckay, C
c34ce3ac-e9e2-40ac-a284-e1e1d681082b
Hamady, Z
545a1c81-276e-4341-a420-aa10aa5d8ca8
Aithal, G P
590c4b29-bf92-446d-b847-e9eb04f4ad7d
Mountford, R
9f045cae-4fb9-4773-939f-814f068ebb38
Ghaneh, P
0ebb95c2-7d0b-471a-855b-c1b0debda486
Hammel, P
b1bfe4f2-aa7d-429e-80d4-98c093f7c1c8
Lerch, M M
4a50f26f-3b2e-493d-baba-66143ac02037
Halloran, C
c026756a-cb4f-473f-a5ce-3f44fe0628fa
Pereira, S P
9c80dd09-6ead-477e-80f0-1d64456aaf15
Greenhalf, W
8a259791-6f89-4ebf-84bf-a81ea681e347
Smith, A
9540a98f-6bad-456a-b694-b8e9b5fe9e15
Sheel, A R G
e8016252-2679-4f8a-b90c-f2095dc5bc1e
Harrison, S
af66a0d9-ce76-4914-a9d8-61f86a998085
Sarantitis, I
1c0c58a4-e71f-492d-a84c-b81356de2794
Nicholson, J A
9043a0a9-5007-4e7a-b8b8-26d6264209c7
Hanna, T
627d1d69-d84a-4f8c-b66e-facbb8a535e5
Grocock, C
de9a400c-08df-4b8b-8565-45a662ae072f
Raraty, M
f4139609-edcc-4e91-a45d-916fb4788e05
Ramesh, J
78330a65-e11d-4a75-96f4-6a36669823ab
Farooq, A
dff97dc3-934c-44e1-9abf-2a77fbda36af
Costello, E
3c0fed5e-fed6-4cfa-b0c1-971fa047d58f
Jackson, R
6287549a-58f1-4ca1-a860-82b757935617
Chapman, M
6b799270-9f6a-4c63-b007-36ecff1a00c1
Carter, R
37d2ed73-da11-47f3-aa1c-c566c1e0814f
Mckay, C
c34ce3ac-e9e2-40ac-a284-e1e1d681082b
Hamady, Z
545a1c81-276e-4341-a420-aa10aa5d8ca8
Aithal, G P
590c4b29-bf92-446d-b847-e9eb04f4ad7d
Mountford, R
9f045cae-4fb9-4773-939f-814f068ebb38
Ghaneh, P
0ebb95c2-7d0b-471a-855b-c1b0debda486
Hammel, P
b1bfe4f2-aa7d-429e-80d4-98c093f7c1c8
Lerch, M M
4a50f26f-3b2e-493d-baba-66143ac02037
Halloran, C
c026756a-cb4f-473f-a5ce-3f44fe0628fa
Pereira, S P
9c80dd09-6ead-477e-80f0-1d64456aaf15
Greenhalf, W
8a259791-6f89-4ebf-84bf-a81ea681e347
Smith, A
9540a98f-6bad-456a-b694-b8e9b5fe9e15

Sheel, A R G, Harrison, S, Sarantitis, I, Nicholson, J A, Hanna, T, Grocock, C, Raraty, M, Ramesh, J, Farooq, A, Costello, E, Jackson, R, Chapman, M, Carter, R, Mckay, C, Hamady, Z, Aithal, G P, Mountford, R, Ghaneh, P, Hammel, P, Lerch, M M, Halloran, C, Pereira, S P, Greenhalf, W and Smith, A (2019) Identification of Cystic Lesions by Secondary Screening of Familial Pancreatic Cancer (FPC) Kindreds Is Not Associated with the Stratified Risk of Cancer. American Journal of Gastroenterology, 114 (1), 155-164. (doi:10.1038/s41395-018-0395-y).

Record type: Article

Abstract

OBJECTIVES: Intraductal papillary mucinous neoplasms (IPMNs) are associated with risk of pancreatic ductal adenocarcinoma (PDAC). It is unclear if an IPMN in individuals at high risk of PDAC should be considered as a positive screening result or as an incidental finding. Stratified familial pancreatic cancer (FPC) populations were used to determine if IPMN risk is linked to familial risk of PDAC.

METHODS: This is a cohort study of 321 individuals from 258 kindreds suspected of being FPC and undergoing secondary screening for PDAC through the European Registry of Hereditary Pancreatitis and Familial Pancreatic Cancer (EUROPAC). Computerised tomography, endoscopic ultrasound of the pancreas and magnetic resonance imaging were used. The risk of being a carrier of a dominant mutation predisposing to pancreatic cancer was stratified into three even categories (low, medium and high) based on: Mendelian probability, the number of PDAC cases and the number of people at risk in a kindred.

RESULTS: There was a median (interquartile range (IQR)) follow-up of 2 (0-5) years and a median (IQR) number of investigations per participant of 4 (2-6). One PDAC, two low-grade neuroendocrine tumours and 41 cystic lesions were identified, including 23 IPMN (22 branch-duct (BD)). The PDAC case occurred in the top 10% of risk, and the BD-IPMN cases were evenly distributed amongst risk categories: low (6/107), medium (10/107) and high (6/107) (P = 0.63).

CONCLUSIONS: The risk of finding BD-IPMN was independent of genetic predisposition and so they should be managed according to guidelines for incidental finding of IPMN.

This record has no associated files available for download.

More information

Published date: January 2019
Keywords: Adult, Aged, Aged, 80 and over, Carcinoma/epidemiology, Cohort Studies, Early Detection of Cancer, Europe/epidemiology, Family, Female, Genetic Predisposition to Disease, Humans, Male, Middle Aged, Pancreatic Neoplasms/epidemiology, Pedigree, Registries, Risk Factors, Young Adult

Identifiers

Local EPrints ID: 455122
URI: http://eprints.soton.ac.uk/id/eprint/455122
ISSN: 0002-9270
PURE UUID: fb88c7e9-e081-4557-89b7-d87380c24c32
ORCID for Z Hamady: ORCID iD orcid.org/0000-0002-4591-5226

Catalogue record

Date deposited: 10 Mar 2022 17:32
Last modified: 17 Mar 2024 04:12

Export record

Altmetrics

Contributors

Author: A R G Sheel
Author: S Harrison
Author: I Sarantitis
Author: J A Nicholson
Author: T Hanna
Author: C Grocock
Author: M Raraty
Author: J Ramesh
Author: A Farooq
Author: E Costello
Author: R Jackson
Author: M Chapman
Author: R Carter
Author: C Mckay
Author: Z Hamady ORCID iD
Author: G P Aithal
Author: R Mountford
Author: P Ghaneh
Author: P Hammel
Author: M M Lerch
Author: C Halloran
Author: S P Pereira
Author: W Greenhalf
Author: A Smith

Download statistics

Downloads from ePrints over the past year. Other digital versions may also be available to download e.g. from the publisher's website.

View more statistics

Atom RSS 1.0 RSS 2.0

Contact ePrints Soton: eprints@soton.ac.uk

ePrints Soton supports OAI 2.0 with a base URL of http://eprints.soton.ac.uk/cgi/oai2

This repository has been built using EPrints software, developed at the University of Southampton, but available to everyone to use.

We use cookies to ensure that we give you the best experience on our website. If you continue without changing your settings, we will assume that you are happy to receive cookies on the University of Southampton website.

×