The University of Southampton
University of Southampton Institutional Repository

A meta-analysis of genome-wide association studies of childhood wheezing phenotypes identifies ANXA1 as a susceptibility locus for persistent wheezing

A meta-analysis of genome-wide association studies of childhood wheezing phenotypes identifies ANXA1 as a susceptibility locus for persistent wheezing
A meta-analysis of genome-wide association studies of childhood wheezing phenotypes identifies ANXA1 as a susceptibility locus for persistent wheezing

Background: many genes associated with asthma explain only a fraction of its heritability. Most genome-wide association studies (GWASs) used a broad definition of 'doctor-diagnosed asthma', thereby diluting genetic signals by not considering asthma heterogeneity. The objective of our study was to identify genetic associates of childhood wheezing phenotypes.

Methods: we conducted a novel multivariate GWAS meta-analysis of wheezing phenotypes jointly derived using unbiased analysis of data collected from birth to 18 years in 9,568 individuals from five UK birth-cohorts.

Results: 44 independent SNPs were associated with early-onset persistent, 25 with preschool remitting, 33 with mid-childhood remitting and 32 with late-onset wheeze. We identified a novel locus on chr9q21.13 (close to annexin 1 (ANXA1), p<6.7×10-9), associated exclusively with early-onset persistent wheeze. We identified rs75260654 as the most likely causative single nucleotide polymorphism (SNP) using Promoter Capture Hi-C loops, and then showed that the risk allele (T) confers a reduction in ANXA1 expression. Finally, in a murine model of house dust mite (HDM)-induced allergic airway disease, we demonstrated that anxa1 protein expression increased and anxa1 mRNA was significantly induced in lung tissue following HDM exposure. Using anxa1-/- deficient mice, we showed that loss of anxa1 results in heightened airway hyperreactivity and Th2 inflammation upon allergen challenge.

Conclusions: targeting this pathway in persistent disease may represent an exciting therapeutic prospect.


Annexin 1, GWAS, asthma, wheeze phenotypes
2050-084X
Granell, Raquel
7b3c9487-b8d2-4462-82ac-e4babc9b60c7
Curtin, John A.
b1f4f316-b8a3-438f-aeab-4c411ab41da2
Haider, Sadia
ed3296e0-288d-49b1-befb-fe4545a7278e
Kitaba, Negusse Tadesse
5e35ae4a-edaa-4b78-bcb6-00628c3b6e83
Mathie, Sara A.
694e5cb2-7801-4350-a322-66372bb06e46
Gregory, Lisa G.
e8e9bcbd-728a-4b50-9494-fbcde8a81034
Yates, Laura L.
d5cf967d-f416-487c-a566-c132f9751a02
Tutino, Mauro
cccfd9bc-988f-4c6b-b9b2-250d55bbda0d
Hankinson, Jenny
d6b90901-1910-48b7-a54d-f7789e93e85b
Perretti, Mauro
7da98728-74b5-4d3d-9bfa-3540f7513491
Vonk, Judith M.
8a2cadb9-0c50-4976-a718-6ccaa83a6b82
Arshad, Hasan S.
917e246d-2e60-472f-8d30-94b01ef28958
Cullinan, Paul
71cec7a8-d4ce-401a-852d-2bbd094c8f13
Fontanella, Sara
6c29b69f-edd6-4414-a8fd-c47241976aa5
Roberts, Graham C.
ea00db4e-84e7-4b39-8273-9b71dbd7e2f3
Koppelman, Gerard H.
db8a0204-1f42-4273-a8a7-8575a43cd21f
Simpson, Angela
5591f945-0ead-46a3-a866-b7bea84a2a83
Turner, Steve W
3e17039b-88bd-42cc-ade2-83a069db640d
Murray, Clare S.
aca69df6-149c-401c-842f-5b2d8042edf1
Lloyd, Clare M.
19c45021-9ced-40dc-921c-364250b183e5
Holloway, John W.
4bbd77e6-c095-445d-a36b-a50a72f6fe1a
Custovic, Adnan
17d8d092-73b8-44fb-bf48-5cea7b29e3fc
UNICORN and Breathing Together Investigators
Granell, Raquel
7b3c9487-b8d2-4462-82ac-e4babc9b60c7
Curtin, John A.
b1f4f316-b8a3-438f-aeab-4c411ab41da2
Haider, Sadia
ed3296e0-288d-49b1-befb-fe4545a7278e
Kitaba, Negusse Tadesse
5e35ae4a-edaa-4b78-bcb6-00628c3b6e83
Mathie, Sara A.
694e5cb2-7801-4350-a322-66372bb06e46
Gregory, Lisa G.
e8e9bcbd-728a-4b50-9494-fbcde8a81034
Yates, Laura L.
d5cf967d-f416-487c-a566-c132f9751a02
Tutino, Mauro
cccfd9bc-988f-4c6b-b9b2-250d55bbda0d
Hankinson, Jenny
d6b90901-1910-48b7-a54d-f7789e93e85b
Perretti, Mauro
7da98728-74b5-4d3d-9bfa-3540f7513491
Vonk, Judith M.
8a2cadb9-0c50-4976-a718-6ccaa83a6b82
Arshad, Hasan S.
917e246d-2e60-472f-8d30-94b01ef28958
Cullinan, Paul
71cec7a8-d4ce-401a-852d-2bbd094c8f13
Fontanella, Sara
6c29b69f-edd6-4414-a8fd-c47241976aa5
Roberts, Graham C.
ea00db4e-84e7-4b39-8273-9b71dbd7e2f3
Koppelman, Gerard H.
db8a0204-1f42-4273-a8a7-8575a43cd21f
Simpson, Angela
5591f945-0ead-46a3-a866-b7bea84a2a83
Turner, Steve W
3e17039b-88bd-42cc-ade2-83a069db640d
Murray, Clare S.
aca69df6-149c-401c-842f-5b2d8042edf1
Lloyd, Clare M.
19c45021-9ced-40dc-921c-364250b183e5
Holloway, John W.
4bbd77e6-c095-445d-a36b-a50a72f6fe1a
Custovic, Adnan
17d8d092-73b8-44fb-bf48-5cea7b29e3fc

Granell, Raquel, Curtin, John A., Haider, Sadia, Kitaba, Negusse Tadesse, Mathie, Sara A., Gregory, Lisa G., Yates, Laura L., Tutino, Mauro, Hankinson, Jenny, Perretti, Mauro, Vonk, Judith M., Arshad, Hasan S., Cullinan, Paul, Fontanella, Sara, Roberts, Graham C., Koppelman, Gerard H., Simpson, Angela, Turner, Steve W, Murray, Clare S., Lloyd, Clare M., Holloway, John W. and Custovic, Adnan , UNICORN and Breathing Together Investigators (2023) A meta-analysis of genome-wide association studies of childhood wheezing phenotypes identifies ANXA1 as a susceptibility locus for persistent wheezing. eLife, 12, [e84315]. (doi:10.7554/eLife.84315).

Record type: Article

Abstract

Background: many genes associated with asthma explain only a fraction of its heritability. Most genome-wide association studies (GWASs) used a broad definition of 'doctor-diagnosed asthma', thereby diluting genetic signals by not considering asthma heterogeneity. The objective of our study was to identify genetic associates of childhood wheezing phenotypes.

Methods: we conducted a novel multivariate GWAS meta-analysis of wheezing phenotypes jointly derived using unbiased analysis of data collected from birth to 18 years in 9,568 individuals from five UK birth-cohorts.

Results: 44 independent SNPs were associated with early-onset persistent, 25 with preschool remitting, 33 with mid-childhood remitting and 32 with late-onset wheeze. We identified a novel locus on chr9q21.13 (close to annexin 1 (ANXA1), p<6.7×10-9), associated exclusively with early-onset persistent wheeze. We identified rs75260654 as the most likely causative single nucleotide polymorphism (SNP) using Promoter Capture Hi-C loops, and then showed that the risk allele (T) confers a reduction in ANXA1 expression. Finally, in a murine model of house dust mite (HDM)-induced allergic airway disease, we demonstrated that anxa1 protein expression increased and anxa1 mRNA was significantly induced in lung tissue following HDM exposure. Using anxa1-/- deficient mice, we showed that loss of anxa1 results in heightened airway hyperreactivity and Th2 inflammation upon allergen challenge.

Conclusions: targeting this pathway in persistent disease may represent an exciting therapeutic prospect.


Text
elife-84315-v1 - Accepted Manuscript
Available under License Creative Commons Attribution.
Download (24MB)
Text
elife-84315-v2 - Version of Record
Available under License Creative Commons Attribution.
Download (6MB)

More information

Accepted/In Press date: 22 May 2023
e-pub ahead of print date: 25 May 2023
Published date: 26 June 2023
Additional Information: Funding Information: UK Medical Research Council Programme Grant MR/S025340/1 and the Wellcome Trust Strategic Award (108,818/15/Z) provided most of the funding for this study.
Keywords: Annexin 1, GWAS, asthma, wheeze phenotypes

Identifiers

Local EPrints ID: 477897
URI: http://eprints.soton.ac.uk/id/eprint/477897
ISSN: 2050-084X
PURE UUID: 14244e3b-b68f-4ac6-800b-8aa9675bbb80
ORCID for Negusse Tadesse Kitaba: ORCID iD orcid.org/0000-0001-7518-9096
ORCID for Graham C. Roberts: ORCID iD orcid.org/0000-0003-2252-1248
ORCID for John W. Holloway: ORCID iD orcid.org/0000-0001-9998-0464

Catalogue record

Date deposited: 16 Jun 2023 16:30
Last modified: 10 Aug 2024 01:51

Export record

Altmetrics

Contributors

Author: Raquel Granell
Author: John A. Curtin
Author: Sadia Haider
Author: Sara A. Mathie
Author: Lisa G. Gregory
Author: Laura L. Yates
Author: Mauro Tutino
Author: Jenny Hankinson
Author: Mauro Perretti
Author: Judith M. Vonk
Author: Hasan S. Arshad
Author: Paul Cullinan
Author: Sara Fontanella
Author: Gerard H. Koppelman
Author: Angela Simpson
Author: Steve W Turner
Author: Clare S. Murray
Author: Clare M. Lloyd
Author: Adnan Custovic
Corporate Author: UNICORN and Breathing Together Investigators

Download statistics

Downloads from ePrints over the past year. Other digital versions may also be available to download e.g. from the publisher's website.

View more statistics

Atom RSS 1.0 RSS 2.0

Contact ePrints Soton: eprints@soton.ac.uk

ePrints Soton supports OAI 2.0 with a base URL of http://eprints.soton.ac.uk/cgi/oai2

This repository has been built using EPrints software, developed at the University of Southampton, but available to everyone to use.

We use cookies to ensure that we give you the best experience on our website. If you continue without changing your settings, we will assume that you are happy to receive cookies on the University of Southampton website.

×