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Multi-cancer early detection test in symptomatic patients referred for cancer investigation in England and Wales (SYMPLIFY): a large-scale, observational cohort study

Multi-cancer early detection test in symptomatic patients referred for cancer investigation in England and Wales (SYMPLIFY): a large-scale, observational cohort study
Multi-cancer early detection test in symptomatic patients referred for cancer investigation in England and Wales (SYMPLIFY): a large-scale, observational cohort study

BACKGROUND: Analysis of circulating tumour DNA could stratify cancer risk in symptomatic patients. We aimed to evaluate the performance of a methylation-based multicancer early detection (MCED) diagnostic test in symptomatic patients referred from primary care.

METHODS: We did a multicentre, prospective, observational study at National Health Service (NHS) hospital sites in England and Wales. Participants aged 18 or older referred with non-specific symptoms or symptoms potentially due to gynaecological, lung, or upper or lower gastrointestinal cancers were included and gave a blood sample when they attended for urgent investigation. Participants were excluded if they had a history of or had received treatment for an invasive or haematological malignancy diagnosed within the preceding 3 years, were taking cytotoxic or demethylating agents that might interfere with the test, or had participated in another study of a GRAIL MCED test. Patients were followed until diagnostic resolution or up to 9 months. Cell-free DNA was isolated and the MCED test performed blinded to the clinical outcome. MCED predictions were compared with the diagnosis obtained by standard care to establish the primary outcomes of overall positive and negative predictive value, sensitivity, and specificity. Outcomes were assessed in participants with a valid MCED test result and diagnostic resolution. SYMPLIFY is registered with ISRCTN (ISRCTN10226380) and has completed follow-up at all sites.

FINDINGS: 6238 participants were recruited between July 7 and Nov 30, 2021, across 44 hospital sites. 387 were excluded due to staff being unable to draw blood, sample errors, participant withdrawal, or identification of ineligibility after enrolment. Of 5851 clinically evaluable participants, 376 had no MCED test result and 14 had no information as to final diagnosis, resulting in 5461 included in the final cohort for analysis with an evaluable MCED test result and diagnostic outcome (368 [6·7%] with a cancer diagnosis and 5093 [93·3%] without a cancer diagnosis). The median age of participants was 61·9 years (IQR 53·4-73·0), 3609 (66·1%) were female and 1852 (33·9%) were male. The MCED test detected a cancer signal in 323 cases, in whom 244 cancer was diagnosed, yielding a positive predictive value of 75·5% (95% CI 70·5-80·1), negative predictive value of 97·6% (97·1-98·0), sensitivity of 66·3% (61·2-71·1), and specificity of 98·4% (98·1-98·8). Sensitivity increased with increasing age and cancer stage, from 24·2% (95% CI 16·0-34·1) in stage I to 95·3% (88·5-98·7) in stage IV. For cases in which a cancer signal was detected among patients with cancer, the MCED test's prediction of the site of origin was accurate in 85·2% (95% CI 79·8-89·3) of cases. Sensitivity 80·4% (95% CI 66·1-90·6) and negative predictive value 99·1% (98·2-99·6) were highest for patients with symptoms mandating investigation for upper gastrointestinal cancer.

INTERPRETATION: This first large-scale prospective evaluation of an MCED diagnostic test in a symptomatic population demonstrates the feasibility of using an MCED test to assist clinicians with decisions regarding urgency and route of referral from primary care. Our data provide the basis for a prospective, interventional study in patients presenting to primary care with non-specific signs and symptoms.

FUNDING: GRAIL Bio UK.

Aged, Cohort Studies, Early Detection of Cancer, England/epidemiology, Female, Humans, Male, Middle Aged, Neoplasms/diagnosis, State Medicine, Wales/epidemiology
1470-2045
733-743
Nicholson, Brian D
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Oke, Jason
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Virdee, Pradeep S
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Harris, Dean A
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O'Doherty, Catherine
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Park, John Es
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Hamady, Zaed
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Sehgal, Vinay
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Millar, Andrew
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Medley, Louise
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Tonner, Sharon
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Vargova, Monika
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Engonidou, Lazarina
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Riahi, Kaveh
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Luan, Ying
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Hiom, Sara
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Kumar, Harpal
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Nandani, Harit
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Kurtzman, Kathryn N
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Yu, Ly-Mee
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Freestone, Clare
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Pearson, Sarah
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Hobbs, Fd Richard
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Perera, Rafael
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Middleton, Mark R
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Nicholson, Brian D
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Oke, Jason
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Virdee, Pradeep S
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Harris, Dean A
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O'Doherty, Catherine
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Park, John Es
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Hamady, Zaed
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Sehgal, Vinay
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Millar, Andrew
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Medley, Louise
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Tonner, Sharon
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Vargova, Monika
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Engonidou, Lazarina
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Riahi, Kaveh
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Luan, Ying
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Hiom, Sara
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Kumar, Harpal
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Nandani, Harit
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Kurtzman, Kathryn N
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Yu, Ly-Mee
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Freestone, Clare
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Pearson, Sarah
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Hobbs, Fd Richard
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Perera, Rafael
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Middleton, Mark R
793f911e-f5a8-48af-8c64-632036105722

Nicholson, Brian D, Oke, Jason, Virdee, Pradeep S, Harris, Dean A, O'Doherty, Catherine, Park, John Es, Hamady, Zaed, Sehgal, Vinay, Millar, Andrew, Medley, Louise, Tonner, Sharon, Vargova, Monika, Engonidou, Lazarina, Riahi, Kaveh, Luan, Ying, Hiom, Sara, Kumar, Harpal, Nandani, Harit, Kurtzman, Kathryn N, Yu, Ly-Mee, Freestone, Clare, Pearson, Sarah, Hobbs, Fd Richard, Perera, Rafael and Middleton, Mark R (2023) Multi-cancer early detection test in symptomatic patients referred for cancer investigation in England and Wales (SYMPLIFY): a large-scale, observational cohort study. Lancet Oncology, 24 (7), 733-743. (doi:10.1016/S1470-2045(23)00277-2).

Record type: Article

Abstract

BACKGROUND: Analysis of circulating tumour DNA could stratify cancer risk in symptomatic patients. We aimed to evaluate the performance of a methylation-based multicancer early detection (MCED) diagnostic test in symptomatic patients referred from primary care.

METHODS: We did a multicentre, prospective, observational study at National Health Service (NHS) hospital sites in England and Wales. Participants aged 18 or older referred with non-specific symptoms or symptoms potentially due to gynaecological, lung, or upper or lower gastrointestinal cancers were included and gave a blood sample when they attended for urgent investigation. Participants were excluded if they had a history of or had received treatment for an invasive or haematological malignancy diagnosed within the preceding 3 years, were taking cytotoxic or demethylating agents that might interfere with the test, or had participated in another study of a GRAIL MCED test. Patients were followed until diagnostic resolution or up to 9 months. Cell-free DNA was isolated and the MCED test performed blinded to the clinical outcome. MCED predictions were compared with the diagnosis obtained by standard care to establish the primary outcomes of overall positive and negative predictive value, sensitivity, and specificity. Outcomes were assessed in participants with a valid MCED test result and diagnostic resolution. SYMPLIFY is registered with ISRCTN (ISRCTN10226380) and has completed follow-up at all sites.

FINDINGS: 6238 participants were recruited between July 7 and Nov 30, 2021, across 44 hospital sites. 387 were excluded due to staff being unable to draw blood, sample errors, participant withdrawal, or identification of ineligibility after enrolment. Of 5851 clinically evaluable participants, 376 had no MCED test result and 14 had no information as to final diagnosis, resulting in 5461 included in the final cohort for analysis with an evaluable MCED test result and diagnostic outcome (368 [6·7%] with a cancer diagnosis and 5093 [93·3%] without a cancer diagnosis). The median age of participants was 61·9 years (IQR 53·4-73·0), 3609 (66·1%) were female and 1852 (33·9%) were male. The MCED test detected a cancer signal in 323 cases, in whom 244 cancer was diagnosed, yielding a positive predictive value of 75·5% (95% CI 70·5-80·1), negative predictive value of 97·6% (97·1-98·0), sensitivity of 66·3% (61·2-71·1), and specificity of 98·4% (98·1-98·8). Sensitivity increased with increasing age and cancer stage, from 24·2% (95% CI 16·0-34·1) in stage I to 95·3% (88·5-98·7) in stage IV. For cases in which a cancer signal was detected among patients with cancer, the MCED test's prediction of the site of origin was accurate in 85·2% (95% CI 79·8-89·3) of cases. Sensitivity 80·4% (95% CI 66·1-90·6) and negative predictive value 99·1% (98·2-99·6) were highest for patients with symptoms mandating investigation for upper gastrointestinal cancer.

INTERPRETATION: This first large-scale prospective evaluation of an MCED diagnostic test in a symptomatic population demonstrates the feasibility of using an MCED test to assist clinicians with decisions regarding urgency and route of referral from primary care. Our data provide the basis for a prospective, interventional study in patients presenting to primary care with non-specific signs and symptoms.

FUNDING: GRAIL Bio UK.

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Published date: July 2023
Additional Information: Copyright © 2023 The Author(s). Published by Elsevier Ltd. This is an Open Access article under the CC BY 4.0 license. Published by Elsevier Ltd.. All rights reserved.
Keywords: Aged, Cohort Studies, Early Detection of Cancer, England/epidemiology, Female, Humans, Male, Middle Aged, Neoplasms/diagnosis, State Medicine, Wales/epidemiology

Identifiers

Local EPrints ID: 485379
URI: http://eprints.soton.ac.uk/id/eprint/485379
ISSN: 1470-2045
PURE UUID: 97dadcea-83f0-42e4-8ed6-029f0859c833
ORCID for Zaed Hamady: ORCID iD orcid.org/0000-0002-4591-5226

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Date deposited: 05 Dec 2023 17:40
Last modified: 21 Mar 2024 03:08

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Contributors

Author: Brian D Nicholson
Author: Jason Oke
Author: Pradeep S Virdee
Author: Dean A Harris
Author: Catherine O'Doherty
Author: John Es Park
Author: Zaed Hamady ORCID iD
Author: Vinay Sehgal
Author: Andrew Millar
Author: Louise Medley
Author: Sharon Tonner
Author: Monika Vargova
Author: Lazarina Engonidou
Author: Kaveh Riahi
Author: Ying Luan
Author: Sara Hiom
Author: Harpal Kumar
Author: Harit Nandani
Author: Kathryn N Kurtzman
Author: Ly-Mee Yu
Author: Clare Freestone
Author: Sarah Pearson
Author: Fd Richard Hobbs
Author: Rafael Perera
Author: Mark R Middleton

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