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The 8p11 myeloproliferative syndrome: a distinct clinical entity caused by constitutive activation of FGFR1

The 8p11 myeloproliferative syndrome: a distinct clinical entity caused by constitutive activation of FGFR1
The 8p11 myeloproliferative syndrome: a distinct clinical entity caused by constitutive activation of FGFR1
Several recurrent translocations that involve chromosome band 8p11 have been described in myeloid malignancies. These translocations target two distinct genes: (1) FGFR1, a receptor tyrosine kinase for fibroblast growth factors, and (2) MOZ, a putative histone acetyltransferase whose precise function remains to be defined. Disruption of FGFR1 is associated with a disease entity known as the 8p11 myeloproliferative syndrome (EMS)/stem cell leukemia-lymphoma syndrome, a chronic myeloproliferative disorder that frequently presents with eosinophilia and associated T-cell lymphoblastic lymphoma. The disease is aggressive and rapidly transforms to acute leukaemia, usually of myeloid phenotype. Currently, only allogeneic stem cell transplantation appears to be effective in eradicating or suppressing the malignant clone. To date, four gene fusions associated with distinct translocations have been described in EMS: the t(8;13)(p11;q12), t(8;9)(p11;q33), t(6;8)(q27;p11) and t(8;22)(p11q22) fuse ZNF198, CEP110, FOP and BCR, respectively, to FGFR1. The resulting fusion proteins have constitutive tyrosine kinase activity and activate multiple signal transduction pathways. These pathways and the fusion proteins are attractive targets for targeted signal transduction therapy
phenotype, pathology, tumor stem cells, therapy, transplantation, humans, disease, lymphoma, protein, fibroblast growth factor, type 1, stem cell transplantation, translocation, genetic, pair 8, etiology, fibroblast growth factors, myeloproliferative disorders, genes, receptor protein-tyrosine kinases, eosinophilia, human, signal transduction, genetics, syndrome, proteins, chromosomes, review, london, metabolism, receptor, cell transplantation, receptors, tyrosine, activity, protein-tyrosine kinase, growth
0001-5792
101-107
Macdonald, D.
de17722c-713a-44d7-b445-6fe5bc0b206a
Reiter, A.
8fc082eb-6b46-4412-86b2-f4c7669f0650
Cross, N.C.
f87650da-b908-4a34-b31b-d62c5f186fe4
Macdonald, D.
de17722c-713a-44d7-b445-6fe5bc0b206a
Reiter, A.
8fc082eb-6b46-4412-86b2-f4c7669f0650
Cross, N.C.
f87650da-b908-4a34-b31b-d62c5f186fe4

Macdonald, D., Reiter, A. and Cross, N.C. (2002) The 8p11 myeloproliferative syndrome: a distinct clinical entity caused by constitutive activation of FGFR1. Acta Haematologica, 107 (2), 101-107. (doi:10.1159/000046639).

Record type: Article

Abstract

Several recurrent translocations that involve chromosome band 8p11 have been described in myeloid malignancies. These translocations target two distinct genes: (1) FGFR1, a receptor tyrosine kinase for fibroblast growth factors, and (2) MOZ, a putative histone acetyltransferase whose precise function remains to be defined. Disruption of FGFR1 is associated with a disease entity known as the 8p11 myeloproliferative syndrome (EMS)/stem cell leukemia-lymphoma syndrome, a chronic myeloproliferative disorder that frequently presents with eosinophilia and associated T-cell lymphoblastic lymphoma. The disease is aggressive and rapidly transforms to acute leukaemia, usually of myeloid phenotype. Currently, only allogeneic stem cell transplantation appears to be effective in eradicating or suppressing the malignant clone. To date, four gene fusions associated with distinct translocations have been described in EMS: the t(8;13)(p11;q12), t(8;9)(p11;q33), t(6;8)(q27;p11) and t(8;22)(p11q22) fuse ZNF198, CEP110, FOP and BCR, respectively, to FGFR1. The resulting fusion proteins have constitutive tyrosine kinase activity and activate multiple signal transduction pathways. These pathways and the fusion proteins are attractive targets for targeted signal transduction therapy

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More information

Published date: 2002
Keywords: phenotype, pathology, tumor stem cells, therapy, transplantation, humans, disease, lymphoma, protein, fibroblast growth factor, type 1, stem cell transplantation, translocation, genetic, pair 8, etiology, fibroblast growth factors, myeloproliferative disorders, genes, receptor protein-tyrosine kinases, eosinophilia, human, signal transduction, genetics, syndrome, proteins, chromosomes, review, london, metabolism, receptor, cell transplantation, receptors, tyrosine, activity, protein-tyrosine kinase, growth

Identifiers

Local EPrints ID: 60002
URI: http://eprints.soton.ac.uk/id/eprint/60002
ISSN: 0001-5792
PURE UUID: fc8bc0e3-3e22-40f2-b340-901e83e6b7c3
ORCID for N.C. Cross: ORCID iD orcid.org/0000-0001-5481-2555

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Date deposited: 02 Sep 2008
Last modified: 16 Mar 2024 03:23

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Contributors

Author: D. Macdonald
Author: A. Reiter
Author: N.C. Cross ORCID iD

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