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Delayed finding of congenital duodenal obstruction following congenital diaphragmatic hernia repair

Delayed finding of congenital duodenal obstruction following congenital diaphragmatic hernia repair
Delayed finding of congenital duodenal obstruction following congenital diaphragmatic hernia repair
Congenital diaphragmatic hernia (CDH) is encountered in just under 1 in 6000 live births, while congenital duodenal obstruction is seen once every 8000 live births. These congenital anomalies have only been reported together as part of the VACTERL syndrome and therefore in isolation represent an incredibly rare occurrence. This is a case report of a girl born at 34 weeks gestation who had an antenatal diagnosis of left CDH. Five days following operative repair of this, there was extensive pneumoperitoneum and pneumothorax. Upper gastrointestinal contrast study showed a perforation of the duodenum and at laparotomy, a duodenal web was found in the fourth part of the duodenum with perforation immediately proximal. Following duodenoduodenostomy, the postoperative recovery was good. She achieved full enteral feeds and was discharged home. This case highlights the importance of considering rare associations if postoperative recovery is not as expected to prevent delay in undergoing definitive treatment.
congenital disorders, paediatric surgery
1757-790X
Bethell, George
c7a62cc1-5573-41f6-ae00-3c11e8219dd4
Fouad, Dina
0f9722f5-e8cb-4146-aaea-2bf090da3c7c
Ogundipe, Enitan
d7a63a27-0df6-41da-806e-2c54573b5218
Choudhry, Mohammed
4f506792-7ba7-48a5-ab36-71b331291cbe
Bethell, George
c7a62cc1-5573-41f6-ae00-3c11e8219dd4
Fouad, Dina
0f9722f5-e8cb-4146-aaea-2bf090da3c7c
Ogundipe, Enitan
d7a63a27-0df6-41da-806e-2c54573b5218
Choudhry, Mohammed
4f506792-7ba7-48a5-ab36-71b331291cbe

Bethell, George, Fouad, Dina, Ogundipe, Enitan and Choudhry, Mohammed (2023) Delayed finding of congenital duodenal obstruction following congenital diaphragmatic hernia repair. BMJ Case Reports, 16 (1), [e253394]. (doi:10.1136/bcr-2022-253394).

Record type: Article

Abstract

Congenital diaphragmatic hernia (CDH) is encountered in just under 1 in 6000 live births, while congenital duodenal obstruction is seen once every 8000 live births. These congenital anomalies have only been reported together as part of the VACTERL syndrome and therefore in isolation represent an incredibly rare occurrence. This is a case report of a girl born at 34 weeks gestation who had an antenatal diagnosis of left CDH. Five days following operative repair of this, there was extensive pneumoperitoneum and pneumothorax. Upper gastrointestinal contrast study showed a perforation of the duodenum and at laparotomy, a duodenal web was found in the fourth part of the duodenum with perforation immediately proximal. Following duodenoduodenostomy, the postoperative recovery was good. She achieved full enteral feeds and was discharged home. This case highlights the importance of considering rare associations if postoperative recovery is not as expected to prevent delay in undergoing definitive treatment.

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Accepted/In Press date: 15 December 2022
Published date: 5 January 2023
Additional Information: Publisher Copyright: © 2023 BMJ Publishing Group. All rights reserved.
Keywords: congenital disorders, paediatric surgery

Identifiers

Local EPrints ID: 473686
URI: http://eprints.soton.ac.uk/id/eprint/473686
ISSN: 1757-790X
PURE UUID: 5fe2892a-3b86-446c-8693-5f3b1985fa33
ORCID for George Bethell: ORCID iD orcid.org/0000-0002-1302-0735

Catalogue record

Date deposited: 27 Jan 2023 17:48
Last modified: 06 Jun 2024 02:15

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Contributors

Author: George Bethell ORCID iD
Author: Dina Fouad
Author: Enitan Ogundipe
Author: Mohammed Choudhry

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